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題 名 | A Poorly Differentiated Ovarian Sertoli-Leydig Cell Tumor in a Thymectomized Myasthenia Gravis Patient--A Case Report=胸腺已切除的重症肌無力病患出現分化不良的卵巢Sertoli-Leydig細胞腫瘤 |
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作 者 | 林浩; 邢福柳; 張簡展照; | 書刊名 | 中華民國婦產科醫學會會刊雜誌 |
卷 期 | 38:4 1999.12[民88.12] |
頁 次 | 頁153-157 |
分類號 | 417.25 |
關鍵詞 | 重症肌無力; 卵巢Sertoli-leydig細胞腫瘤; Myasthenia gravis; Ovarian Sertoli-Leydig cell tumor; |
語 文 | 英文(English) |
中文摘要 | 背景:重症肌無力是一種自體免疫疾病,可能伴隨胸腺外的惡性腫瘤,像是白血病或是網狀內皮系統的惡性肉瘤,不過卻鮮少有婦科方面的惡性腫瘤報告過。在此,我們提出一胸腺已切除的重症肌無力病患出現一個分化不良的卵巢Sertoli-Leydig細胞腫瘤。 病例報告:一位42歲女性病患因次發性無月經一年而到本院求診。這位病患13年前因重症肌無力併胸腺瘤而切除胸腺。電腦斷層發現一8x5公分密度不均勻的腫瘤在右側骨盆腔。開腹後發現一外表完整的右側卵巢瘤,予以手術切除。病理切片顯示為一分化不良的卵巢Sertoli-Leydig細胞腫瘤。病人術後恢復良好,沒有給予任何輔助性化療,目前無復發,已存活達五年之久。 結論:重症肌無力和卵巢Sertoli-Leydig細胞腫瘤的發生或許是一巧合,不過由於胸腺外惡性腫瘤的高發生率,在重症肌無力的病人如發現有骨盆腔腫瘤時,必須考慮是否為惡性腫瘤。 |
英文摘要 | BACKGROUND: Myasthenia gravis, an autoimmune disease, is usually associated with extrathymic malignancies such as leukemia and sarcoma of the reticulo-endothelial system. However, gynecologic malignancy has seldom been reported. Here, we report a thymectomized myasthenia gravis patient presenting a poorly differentiated ovarian Sertoli-Leydig cell tumor. CASE REPORT: A 42-year-old woman was admitted to our hospital because of secondary amenorrhea for 1 year. Thymectomy for thymoma with myasthenia gravis was carried out on this patient 13 years previously. Pelvic computed tomography revealed an 8x5 cm heterogenous mass over the right side of the pelvis. Exploratory laparotomy showed a well-circumscribed right ovarian tumor, and right oophorectomy was carried out. Pathologic examination confirmed a diagnosis of poorly differentiated ovarian Sertoli-Leydig cell tumor. The postoperative course was uneventful and she has been disease free for 5 years with no adjuvant therapy. CONCLUSIONS: The occurrence of myasthenia gravis and ovarian Sertoli-Leydig cell tumor may be a coincidence. However, due to the high incidence of extrathymic malignancies, a diagnosis of ovarian malignancy should be taken into consideration in a myasthenia gravis patient presenting with a pelvic mass. |
本系統中英文摘要資訊取自各篇刊載內容。