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題 名 | Oral Manifestations of Primary Hyperparathyroidism--Case Report=原發性副甲狀腺機能亢進症之口腔表徵--病例報告 |
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作 者 | 陳以蕙; 盧心玉; | 書刊名 | 中華牙醫學雜誌 |
卷 期 | 17:2 1998.06[民87.06] |
頁 次 | 頁96-103 |
分類號 | 416.94 |
關鍵詞 | 原發性副甲狀腺機能亢進症; 囊狀纖維性骨炎; Primary hyperparathyroidism; Osteitis fibrosa cystica; Generalisata; |
語 文 | 英文(English) |
中文摘要 | 原發性副甲狀腺機能亢進症為一副甲狀腺荷爾蒙過量分泌的疾病,造成之影響以 骨骼及腎臟為主。早期症狀可能為骨痛、關節僵直、病理性骨折或腎結石。囊狀纖維性骨炎 則為臨床罕見之嚴重骨骼病變。 本文報告一位六十七歲女性,主訴左下肢變形腫痛致無法行走長達三年,且有全身骨骼 疼痛、多處骨頭變形等症狀。住院診查發現:(1)全身多處骨變形,骨質疏鬆(2)左上肢 病理性骨折(3)左腎結石(4)高血鈣、低血磷、鹼性磷酸脢及副甲狀腺荷爾蒙過高(5) 有便祕、多尿病史。X光診查發現:下肢長骨呈骨膜下吸收合併囊腫性病灶。口腔壞吸收, 上下顎牙齒周圍骨板消失,左下顎呈多房性囊腫。電腦斷層攝影則顯示:左下顎骨呈均勻富 含血液、膨脹性骨溶性病變。於左下顎骨腫瘤處切片之病理報告發現:骨樑架構嚴重破壞, 組織中充滿多核巨細胞及滲出血管外之紅血球,符合典型囊狀纖維性骨炎之診斷,起因則為 副甲狀腺腺瘤所致。目前因副甲狀腺機能亢進症造成嚴重之骨骼病變已相當少見,然而對於 因此症造成之顎骨病變仍應保持警覺。本文特別回顧文獻提出診斷重點以供參考。 |
英文摘要 | Primary hyperparathyroidism is a generalized disorder of calcium, phosphate, and bone metabolism. Manifestations primarily involve the kidneys and skeletal system; however, presentation as severe osteoporotic change or osteitis fibrosa cyrstica is rare. This article reports the case of a 67-year-old woman who experienced progressive malocclusion due to swelling of the left mandible, bilateral lower leg weakness, lower back pain, and multiple deformities involving her left mandible, right temporal bone, and left lower extremity for about 3 years. Based on nclinical examination, laboratory tests and radiographic findings, an impression of primary hyperparathyroidism with osteitis fibrosa cystica was established. A bone biopsy of the left mandible confirmed the diagnosis of hyperparathyroidism. As osteitis fibrosa cystica is uncommon, awareness of the maxillofacial manifestations of primary hyperparathyroidism is important for detection of the disease. This case report emphasizes the pertinent oral findings and oral biopsy which may provide aid for diagnosis. |
本系統中英文摘要資訊取自各篇刊載內容。