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題 名 | Response of Epstein-Barr Virus-Associated Ki-1狇Anaplastic Large Cell Lymphoma to 13-Cis Retinoic Acid and Interferon Alpha=維甲酸及干擾素對EB病毒相關的未分化大細胞淋巴瘤的反應 |
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作 者 | 陳功深; 張義芳; 張明志; 詹錕鋙; | 書刊名 | 臺灣醫學會雜誌 |
卷 期 | 97:6 1998.06[民87.06] |
頁 次 | 頁420-424 |
分類號 | 415.6 |
關鍵詞 | 維甲酸; 干擾素; EB病毒; 未分化大細胞淋巴瘤; Epstein-barr virus; Interferon alpha; Hemophagocytic syndrome; Anaplastic large cell lymphoma; Peripheral t-cell lymphoma; 13-cis retinoic acid; |
語 文 | 英文(English) |
英文摘要 | The response of peripheral T-cell lymphoma to 13-cis retinoic acid (13-cis-RA) has been well established, especially in Ki-l□ anaplastic large cell lymphoma (ALCL) confined to the skin. Here, we report the use of 13-cis-RA in combination with interferon alpha in a patient with refractory ALCL. The patient, an 18-year-old man, suffered from retroperitoneal, hepatic, and splenic ALCL. Reactive hemophagocytic syndrome also developed. Active Epstein-Barr virus infection was demonstrated by serologic tests and in situ hybridization of Epstein- Barr virus early RNA-1. Although high-dose intravenous immunoglobulin (IgG), etoposide, and steroids were administered, only chemotherapy (methotrexate, bleomycin, doxorubicin, cyclophosphamide, vincristine, and dexamethasone) successfully controlled the progress of hemophagocytosis. However, the retroperitoneal mass and splenic tumor did not show a satisfactory response to three cycles of chemotherapy. Hence, interferon 4.5 MU/m□ every other day with 13-cis-RA 1mg/kg/day was instituted. Abdominal computed tomogram after 58 days of treatment revealed that the tumor had significantly reduced in size. Bone marrow biopsy demonstrated alleviation of hemophagocytosis as well. However, lymphoma cells had begun to infiltrate the bone marrow, Our findings suggest that 13-cis-RA and interferon alpha may be partially effective in treating ALCL. |
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