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題 名 | Panniculitis Associated with Wrist Drop in a Rheumatoid Arthritis Patient=脂層炎併發垂腕症出現在一類風濕性關節炎病人 |
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作 者 | 林仙明; 郭樂明; | 書刊名 | 中華民國風濕病雜誌 |
卷 期 | 14:1/2 民86.05 |
頁 次 | 頁31-41 |
分類號 | 415.695 |
關鍵詞 | 類風濕性關節炎; Septal panniculitis; Mononeuritis multiplex; Wrist drop; Rheumatiod vasculitis; Rheumatioid arthritis; |
語 文 | 英文(English) |
中文摘要 | 脂層炎常出現在結締組織疾病如紅班性狼瘡、皮肌炎、硬皮症等,但出現在類風濕性關節炎病人,非常少見。從過去文獻回顧,只有六例報告。本文報告一位三十四歲男性病人,患有類風濕性關節炎病史二年之久。 住院前五天因右前臂皮膚出現 8 × 6 × 2 公分皮下結節,同時有紅腫熱痛症狀。另外合併有右手腕下垂。從皮膚病灶作病理切片檢查碓實為中隔性脂層炎。右前臂神經電生理學檢查發現為橈神經軸索變性,但前臂肌肉肌電圖檢查卻是正常。 血清學檢查發現高效價類風濕性因子及補體下降。 經類固醇及口服Cyclophosphamide 治療後,皮膚病灶在一週後好轉,而垂腕症狀在六週後改善, 但右前臂皮下脂層卻明顥萎縮。脂層炎併發垂腕症出現在類風濕性關節炎病人,同時血清學檢查發現 高效價類風濕性因子及補體下降提示免疫複合體在致病機轉上扮演重要角色。 |
英文摘要 | Panniculitis has been reported in connective tissue diseases, such as lupus erythematosus, dermatomyositis and scleroderma but seldomly reported in rheumatoid arthritis (RA) and particularly wrist drop develop. We report a case of 34 year-old man with two years history of RA and admitted recently due to right wrist drop associated with a subcutaneous nodule in size of 8×6×2 cm over the right forearm for five days. Skin biopsy from the nodule demonstrated septal panniculitis. Electrophysiologic studies of the right forearm showed axonal degeneration of the right radial nerve but electromyography studies was normal which was compatible with the diagnosis of mononeuritis multiplex. Laboratory findings showed high serum titers of rheumatoid factors and hypocomplementemia. He was treated with systemic corticosteroid and cyclophosphamide orally. Subcutaneous nodule was resolved within one week of treatment and remarkable subcutaneous fat atrophy of the affected right forearm was noticed one month later. Right wrist function recovered within six weeks after treatment. Panniculitis and mononeuritis multiplex complicating RA with high serum titer of rheumatoid factor and hypocomplementemia which suggest that immune complexes deposition may play an important role in the pathogenesis of the disease. |
本系統中英文摘要資訊取自各篇刊載內容。