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題 名 | Double Pathology of the Odontogenic Tumor: Odontogenic Myxoma Accompanied by a Calcifying Odontogenic Cyst--A Case Report=雙重診斷之齒源性腫瘤:齒源性粘液瘤伴有鈣化性齒源性囊腫--病例報告 |
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作 者 | 蔡孟君; 吳哲輝; 張明智; 李嘉鐸; 游竣傑; 黃鵬宇; 林宏政; | 書刊名 | 臺灣口腔顎面外科學會雜誌 |
卷 期 | 30:4 2019.12[民108.12] |
頁 次 | 頁268-275 |
分類號 | 416.954 |
關鍵詞 | 雙重診斷; 齒源性粘液瘤; 鈣化齒源性囊腫; Double pathology; Odontognic myxoma; Calcifying odontogenic cyst; |
語 文 | 英文(English) |
中文摘要 | 齒源性粘液瘤是一種良性腫瘤,但擁有局部侵略性。除了齒源性外,粘液瘤很少發生於骨內,而齒源性粘液瘤被認為源自牙胚的間充質部分。臨床上,其特徵為生長緩慢且無痛擴張,並不具有遠端轉移的特性。鈣化性齒源性囊腫為Gorlin在1962年發現命名為Gorlin囊腫,同時也是一種罕見的良性病變。它是齒源性上皮細胞的擴散,組織病理切片中亦可見到分散的幽靈細胞及內層的鈣化。鈣化性齒源性囊腫可能單獨發生也可能與其他齒源性腫瘤同時發生,其中齒瘤占了24%。同時有兩種病理診斷的口腔腫瘤極為罕見。我們的病例報告即是一位健康無其他疾病的19歲台灣女性的上頷骨右側腫瘤,診斷為齒源性粘液瘤和鈣化齒源性囊腫。其臨床表現為生長緩慢,無痛擴張且無轉移性的腫瘤。放射線影像顯示了一個明確的可透性病變,並含有不透射線的物質。組織學上包括一個大的囊腫和牙齒結構。因此,我們進行了腫瘤剜除手術,結果出現了雙重病理診斷。據我們所知,齒源性腫瘤中雙重病理診斷的病例很少發生。我們對於此類的病例提出討論與處置方式,並簡要回顧了當前的文獻,以建立齒源性粘液瘤與鈣化齒源性囊腫相關的臨床意義的概念。 |
英文摘要 | Odontogenic myxoma (OM) is a benign but locally aggressive neoplasm. Myxomas rarely occur intraosseously, except for odontogenic myxoma. Odontogenic myxoma is considered to be derived from the mesenchymal portion of the tooth germ. Clinically, it is slow-growing, an expansile, painless, and non-metastasizing tumor, which is found chiefly in the mandible. The calcifying odontogenic cyst (COC) was previously described by Gorlin et al. in 1962 as Gorlin cyst. It is also an uncommon benign lesion, which is a proliferation of the odontogenic epithelium characterized by scattered nests of ghost cells, and calcifications that may form the lining of a cyst. The COC is solitary or occurs with odontomas (24%) or other odontogenic tumors. Two different pathologic lesions in a tumor are unusual. We reported a maxillary tumor composed of an odontogenic myxoma and a calcifying odontogenic cyst on the right side of the maxilla of a 19-year-old Taiwanese woman who denied any underlying disease. The clinical appearance was a painless, expansile, slow-growing and non-metastasizing tumor; however, the radiography revealed a well-defined radiolucent lesion containing radiopaque substances and the histopathologic result of an incisional biopsy consisted of a large cyst as well as tooth structures. Therefore, we performed enucleation of the lesion and the results came out to be a double pathologic diagnosis. The occurrence of double pathology in an odontogenic tumor, to our knowledge, was seldom reported. We discussed the management for this combined lesion with a brief review of the current literature in order to build a concept of the clinical significance of an association of odontogenic myxomas with calcifying odontogenic cysts, which still remains unknown. |
本系統中英文摘要資訊取自各篇刊載內容。